Radiologically occult cervical intradural dermal sinus tract: a case report and review of literature

Abstract

We report the unusual case of a 7-month-old girl presenting with congenital cervical dermal sinus tract in which the intradural tract was not detected on preoperative imaging and was identified intraoperatively. Considering possible devastating sequelae of infection, excision of dermal sinus tract might be justified even in the case with radiologically undetected intradural tract.

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References

  1. 1.

    Shen WC, Chiou TL, Lin TY (2000) Dermal sinus with dermoid cyst in the upper cervical spine: case note. Neuroradiology 42:51–53. https://doi.org/10.1007/s002340050013

    CAS  Article  PubMed  Google Scholar 

  2. 2.

    Wang KC, Yang HJ, Oh CW et al (1993) Spinal congenital dermal sinus--experience of 5 cases over a period of 10 years. J Korean Med Sci 8:341–347

    CAS  Article  Google Scholar 

  3. 3.

    Ceddia A, Di Rocco C, Pastorelli G (1990) The congenital cervical dermal sinus. A clinical case report and review of the literature. Minerva Pediatr 42:553–558

    CAS  PubMed  Google Scholar 

  4. 4.

    Simon JK, Lazareff JA, Diament MJ, Kennedy WA (2003) Intramedullary abscess of the spinal cord in children: a case report and review of the literature. Pediatr Infect Dis J 22:186–192. https://doi.org/10.1097/01.inf.0000048910.19136.49

    Article  PubMed  Google Scholar 

  5. 5.

    Dagcinar A, Konya D, Akakin A et al (2008) Congenital dermal sinus of the cervical spine in an adult. J Clin Neurosci Off J Neurosurg Soc Australas 15:73–76. https://doi.org/10.1016/j.jocn.2006.05.022

    Article  Google Scholar 

  6. 6.

    Mrowczynski OD, Lane JR, Shoja MM et al (2018) Double dermal sinus tracts of the cervical and thoracic regions: a case in a 3-year-old child and review of the literature. Childs Nerv Syst ChNS Off J Int Soc Pediatr Neurosurg 34:987–990. https://doi.org/10.1007/s00381-017-3707-4

    Article  Google Scholar 

  7. 7.

    Nicola Z, Antonio C, De Tommasi A (2014) Cervical dermal sinus complicated with intramedullary abscess in a child: case report and review of literature. Eur Spine J Off Publ Eur Spine Soc Eur Spinal Deform Soc Eur Sect Cerv Spine Res Soc 23(Suppl 2):192–196. https://doi.org/10.1007/s00586-013-2930-2

    Article  Google Scholar 

  8. 8.

    Shah RK, Chaljub G, Swischuk LE (2003) Lower cervical dermal sinus tract and associated intraspinal abscess causing meningitis in a child. Emerg Radiol 10:160–162. https://doi.org/10.1007/s10140-003-0304-5

    Article  PubMed  Google Scholar 

  9. 9.

    Barkovich AJ, Edwards MS, Cogen PH (1991) MR evaluation of spinal dermal sinus tracts in children. AJNR Am J Neuroradiol 12:123–129

    CAS  PubMed  Google Scholar 

  10. 10.

    Tisdall MM, Hayward RD, Thompson DNP (2015) Congenital spinal dermal tract: how accurate is clinical and radiological evaluation? J Neurosurg Pediatr 15:651–656. https://doi.org/10.3171/2014.11.PEDS14341

    Article  PubMed  Google Scholar 

  11. 11.

    Lee SM, Cheon J-E, Choi YH et al (2017) Limited dorsal myeloschisis and congenital dermal sinus: Comparison of clinical and MR imaging features. Am J Neuroradiol 38:176–182. https://doi.org/10.3174/ajnr.A4958

    CAS  Article  PubMed  Google Scholar 

  12. 12.

    Martínez-Lage JF, Almagro MJ, Ferri-Ñiguez B et al (2011) Spinal dermal sinus and pseudo-dermal sinus tracts: two different entities. Childs Nerv Syst ChNS Off J Int Soc Pediatr Neurosurg 27:609–616. https://doi.org/10.1007/s00381-010-1308-6

    Article  Google Scholar 

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Correspondence to Hideki Ogiwara.

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Mukai, T., Usami, K., Ishisaka, E. et al. Radiologically occult cervical intradural dermal sinus tract: a case report and review of literature. Childs Nerv Syst (2020). https://doi.org/10.1007/s00381-020-04673-9

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Keywords

  • Dermal sinus tract
  • Intradural tract
  • Cervical