Multiple Enlarged Aneurysms in Primary Racemose Hemangioma of the Bronchial Artery: Successful Prophylactic Transcatheter Arterial Embolization Using N-butyl-2-cyanoacrylate and Coils

  • Atsushi Saiga
  • Toshihiko Sugiura
  • Takashi Higashide
  • Satoshi Tsuchiya
  • Akira Nishiyama
  • Yoshihiro Kubota
  • Takuro Horikoshi
  • Takashi Uno
Case Report


An asymptomatic 48-year-old man presented with multiple aneurysms in a primary racemose hemangioma of the right bronchial artery. Bronchial arteriography revealed a tortuous artery with four fusiform aneurysms of varying sizes and aneurysmal dilatation with marked thrombus formation in the long segment of the distal portion. Because the tip of catheter could not pass beyond the aneurysmal dilatation, we performed balloon-occluded embolization using a mixture of N-butyl-2-cyanoacrylate (NBCA) and iodized oil. For four other aneurysms, we performed embolization using a coil alone or with NBCA. After 6 months, right bronchial arteriography revealed no enhancement of the aneurysms. Despite the rarity of this procedure, embolization with NBCA is a good option for bronchial artery aneurysm embolization.


Primary racemose hemangioma of the bronchial artery Bronchial artery aneurysm Transcatheter arterial embolization N-butyl-2-cyanoacrylate 


Compliance with Ethical Standards

Conflict of interest

All authors declare that they have no conflicts of interest.

Ethical Approval

This article does not contain any studies with human participants or animals performed by any of the authors. For this type of study, formal consent is not required.

Informed Consent

Informed consent was obtained from the patient in the study.


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Copyright information

© Springer Science+Business Media, LLC, part of Springer Nature and the Cardiovascular and Interventional Radiological Society of Europe (CIRSE) 2018

Authors and Affiliations

  1. 1.Department of RadiologyChiba University HospitalChiba CityJapan
  2. 2.Department of RespirologyChiba University HospitalChiba CityJapan
  3. 3.Department of RadiologyJapanese Red Cross Narita HospitalNarita CityJapan
  4. 4.Department of Diagnostic Radiology and Radiation OncologyGraduate School of Medicine, Chiba UniversityChiba CityJapan

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