A case report of atopic myelitis mimicking anterior spinal artery syndrome

  • Kosuke MatsuzonoEmail author
  • Masayuki Suzuki
  • Shigeru Fujimoto
Letter to the Editor


Atopic myelitis (AM) is a rare condition, with almost 100 cases reported in Japan [1] and a few cases reported in Europe [2]. AM consists of localized, persistent inflammation of the spinal cord [3] associated with high levels of immunoglobulin E (IgE) and mite antigen-specific IgE [4]. Most AM lesions detected with magnetic resonance imaging (MRI) are in the posterior or central portion of the spinal cord [5], although involvement of anterior horn cells has been reported [6]. Herein, we report the case of a man who appeared to have anterior spinal artery syndrome (ASAS) because of an anterior lesion in the thoracic cord, but who was finally diagnosed with AM.

Case presentation

A 46-year-old man developed monoparesis with sensory disturbance in the left leg. Urinary retention developed 1 day after the onset of monoparesis. The patient’s symptoms gradually worsened, but the etiology remained undetermined. The patient was admitted to our hospital 7 days after the onset of...


Authors’ contributions

KM and MS were the attending doctors in the present case. KM drafted the manuscript. SF conceived the study, participated in its coordination, and helped to draft the manuscript. All authors read and approved the final manuscript.

Compliance with ethical standards

Conflict of interest

The authors declare that they have no competing interests.

Ethical standards

Informed consent was obtained from the patient described in this article.


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Copyright information

© Fondazione Società Italiana di Neurologia 2019

Authors and Affiliations

  1. 1.Division of Neurology, Department of MedicineJichi Medical University School of MedicineShimotsukeJapan

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